In all susceptible patients with suspected mucormycosis, promptly starting appropriate antifungal therapy and surgical debridement is essential for good outcomes in this otherwise rapidly fatal disease.[4]Centers for Disease Control and Prevention. Mucormycosis: clinical overview of mucormycosis. Apr 2024 [internet publication].
https://www.cdc.gov/mucormycosis/hcp/clinical-overview/index.html
In appropriate circumstances, immune function should be reconstituted if possible to improve outcome. This may require recovery of neutropenia, tapering of corticosteroids, or reversal of acidosis. Available data suggest that a delay in initiating treatment of 6 days or longer after diagnosis results in a twofold increase in mortality at 12 weeks after diagnosis.[55]Spellberg B, Ibrahim AS. Recent advances in the treatment of mucormycosis. Curr Infect Dis Rep. 2010 Nov;12(6):423-9.
https://www.ncbi.nlm.nih.gov/pmc/articles/PMC2947016
http://www.ncbi.nlm.nih.gov/pubmed/21308550?tool=bestpractice.com
Surgery
Surgery is key to remove necrotic tissue and curb the spread of infection. Necrosis occurs due to vascular thrombosis, which precludes adequate delivery of antifungal agents.[3]Spellberg B, Edwards J Jr, Ibrahim A. Novel perspectives on mucormycosis: pathophysiology, presentation, and management. Clin Microbiol Rev. 2005 Jul;18(3):556-69.
https://www.ncbi.nlm.nih.gov/pmc/articles/PMC1195964
http://www.ncbi.nlm.nih.gov/pubmed/16020690?tool=bestpractice.com
Surgery plays a vital role in all forms of mucormycosis whenever feasible; however, some patients may be too unwell to undergo surgery.[12]Cornely OA, Alastruey-Izquierdo A, Arenz D, et al. Global guideline for the diagnosis and management of mucormycosis: an initiative of the European Confederation of Medical Mycology in cooperation with the Mycoses Study Group Education and Research Consortium. Lancet Infect Dis. 2019 Dec;19(12):e405-21.
https://pmc.ncbi.nlm.nih.gov/articles/PMC8559573
http://www.ncbi.nlm.nih.gov/pubmed/31699664?tool=bestpractice.com
In patients with rhino-orbito-cerebral mucormycosis, extensive surgical debridement frequently requires removing the paranasal sinuses along with disease from the nose and the orbit, if involved.[56]Arndt S, Aschendorff A, Echternach M, et al. Rhino-orbital-cerebral mucormycosis and aspergillosis: differential diagnosis and treatment. Eur Arch Otorhinolaryngol. 2009 Jan;266(1):71-6.
http://www.ncbi.nlm.nih.gov/pubmed/18470529?tool=bestpractice.com
In patients with isolated cutaneous disease due to burns or in trauma patients, aggressive surgical debridement to remove all necrotic tissue is essential.
Antifungal induction therapy
Antifungal therapy is recommended in addition to surgery, or as a first-line treatment in those who are not suitable for surgery.
Amphotericin-B is recommended first line.[12]Cornely OA, Alastruey-Izquierdo A, Arenz D, et al. Global guideline for the diagnosis and management of mucormycosis: an initiative of the European Confederation of Medical Mycology in cooperation with the Mycoses Study Group Education and Research Consortium. Lancet Infect Dis. 2019 Dec;19(12):e405-21.
https://pmc.ncbi.nlm.nih.gov/articles/PMC8559573
http://www.ncbi.nlm.nih.gov/pubmed/31699664?tool=bestpractice.com
Amphotericin-B belongs to the polyene class of antifungals and is the most effective therapy against agents of mucormycosis. Liposomal and lipid formulations are preferred over the deoxycholate formulation as they minimize renal dysfunction, infusion reactions, and toxicity. Amphotericin-B deoxycholate is effective but should be avoided; its use is limited by substantial toxicity in the doses and treatment durations needed for mucormycosis. It should only be used in settings where no other antifungal treatment options are available.[12]Cornely OA, Alastruey-Izquierdo A, Arenz D, et al. Global guideline for the diagnosis and management of mucormycosis: an initiative of the European Confederation of Medical Mycology in cooperation with the Mycoses Study Group Education and Research Consortium. Lancet Infect Dis. 2019 Dec;19(12):e405-21.
https://pmc.ncbi.nlm.nih.gov/articles/PMC8559573
http://www.ncbi.nlm.nih.gov/pubmed/31699664?tool=bestpractice.com
Treatment with liposomal amphotericin-B has been reported to result in better survival in cancer patients, compared with amphotericin-B deoxycholate (67% versus 39%).[57]Dan M. Mucormycosis of the head and neck. Curr Infect Dis Rep. 2011 Apr;13(2):123-31.
http://www.ncbi.nlm.nih.gov/pubmed/21365375?tool=bestpractice.com
Liposomal amphotericin-B also appears to be more effective in rhinocerebral disease.[57]Dan M. Mucormycosis of the head and neck. Curr Infect Dis Rep. 2011 Apr;13(2):123-31.
http://www.ncbi.nlm.nih.gov/pubmed/21365375?tool=bestpractice.com
Liposomal amphotericin-B is more effective than the lipid formulation in treating central nervous system disease, making it the first-line agent in central nervous system mucormycosis, with the lipid formulation a second-line agent.[57]Dan M. Mucormycosis of the head and neck. Curr Infect Dis Rep. 2011 Apr;13(2):123-31.
http://www.ncbi.nlm.nih.gov/pubmed/21365375?tool=bestpractice.com
Posaconazole or isavuconazonium (a prodrug of isavuconazole) are azole antifungals and may be used intravenously as a second-line treatment. They are the preferred treatments in patients with pre-existing renal compromise as amphotericin-B can cause nephrotoxicity, even lipid or liposomal formulations.[12]Cornely OA, Alastruey-Izquierdo A, Arenz D, et al. Global guideline for the diagnosis and management of mucormycosis: an initiative of the European Confederation of Medical Mycology in cooperation with the Mycoses Study Group Education and Research Consortium. Lancet Infect Dis. 2019 Dec;19(12):e405-21.
https://pmc.ncbi.nlm.nih.gov/articles/PMC8559573
http://www.ncbi.nlm.nih.gov/pubmed/31699664?tool=bestpractice.com
Isavuconazonium has been approved by the Food and Drug Administration (FDA) for the treatment of invasive mucormycosis. It has less nephrotoxic potential than other intravenous azoles.[58]Falci DR, Pasqualotto AC. Profile of isavuconazole and its potential in the treatment of severe invasive fungal infections. Infect Drug Resist. 2013 Oct 22;6:163-74.
https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3810441
http://www.ncbi.nlm.nih.gov/pubmed/24187505?tool=bestpractice.com
No therapeutic drug monitoring is needed.
Breakthrough infection with Rhizopus oryzae has been reported in patients on posaconazole prophylaxis.[59]Enoch DA, Aliyu SH, Sule O, et al. Posaconazole for the treatment of mucormycosis. Int J Antimicrob Agents. 2011 Dec;38(6):465-73.
http://www.ncbi.nlm.nih.gov/pubmed/21782392?tool=bestpractice.com
Posaconazole requires about 1 week to reach steady-state serum concentrations and, hence, should not be the initial therapy for a patient with mucormycosis. Consider therapeutic monitoring of posaconazole blood levels in the following:
No clinical response is noted
In pediatric patients
If there is mucositis, malabsorption, or inability to tolerate high fat meals
With a resistant organism
There is infection at sanctuary sites
There is coprescribing with proton-pump inhibitors, anticonvulsants, H2 antagonists, or gastric motility agents.
Trough levels can be measured after 5-7 days of initiating therapy with a goal of >1 mg/L.[1]Pham D, Howard-Jones AR, Sparks R, et al. Epidemiology, modern diagnostics, and the management of mucorales infections. J Fungi (Basel). 2023 Jun 12;9(6):659.
https://pmc.ncbi.nlm.nih.gov/articles/PMC10304757
http://www.ncbi.nlm.nih.gov/pubmed/37367595?tool=bestpractice.com
In a study of patients with graft-versus-host disease following hematopoietic stem cell transplant, the patients who developed invasive fungal infections (IFIs) had median and peak posaconazole levels of 0.611 micrograms/mL and 0.635 micrograms/mL, respectively, while the patients without IFIs had median and peak posaconazole levels of 0.922 micrograms/mL and 1.36 micrograms/mL, respectively.[59]Enoch DA, Aliyu SH, Sule O, et al. Posaconazole for the treatment of mucormycosis. Int J Antimicrob Agents. 2011 Dec;38(6):465-73.
http://www.ncbi.nlm.nih.gov/pubmed/21782392?tool=bestpractice.com
[60]Andes D, Pascual A, Marchetti O. Antifungal therapeutic drug monitoring: established and emerging indications. Antimicrob Agents Chemother. 2009 Jan;53(1):24-34.
https://www.ncbi.nlm.nih.gov/pmc/articles/PMC2612175
http://www.ncbi.nlm.nih.gov/pubmed/18955533?tool=bestpractice.com
Amphotericin-B is associated with nephrotoxicity, hypokalemia, anemia, and infusion-related adverse reactions. Azole antifungals are hepatotoxic (monitor liver function during therapy) and undergo a number of potential drug-drug interactions. Data in pregnant women with mucormycosis are not widely available.
The regimens presented in this topic depend on the geographical location as not all recommended treatments have regulatory approval in all regions or are available for use in all clinical settings.[12]Cornely OA, Alastruey-Izquierdo A, Arenz D, et al. Global guideline for the diagnosis and management of mucormycosis: an initiative of the European Confederation of Medical Mycology in cooperation with the Mycoses Study Group Education and Research Consortium. Lancet Infect Dis. 2019 Dec;19(12):e405-21.
https://pmc.ncbi.nlm.nih.gov/articles/PMC8559573
http://www.ncbi.nlm.nih.gov/pubmed/31699664?tool=bestpractice.com
Antifungal maintenance therapy
Further treatment depends on the initial clinical response and whether the patient experiences toxicity from the initial treatment regimens.
Once the patient is stable or has a partial response, either continue the first-line regimen or change to a suitable oral regimen.[12]Cornely OA, Alastruey-Izquierdo A, Arenz D, et al. Global guideline for the diagnosis and management of mucormycosis: an initiative of the European Confederation of Medical Mycology in cooperation with the Mycoses Study Group Education and Research Consortium. Lancet Infect Dis. 2019 Dec;19(12):e405-21.
https://pmc.ncbi.nlm.nih.gov/articles/PMC8559573
http://www.ncbi.nlm.nih.gov/pubmed/31699664?tool=bestpractice.com
Oral isavuconazonium or posaconazole are the preferred options for step-down treatment.[12]Cornely OA, Alastruey-Izquierdo A, Arenz D, et al. Global guideline for the diagnosis and management of mucormycosis: an initiative of the European Confederation of Medical Mycology in cooperation with the Mycoses Study Group Education and Research Consortium. Lancet Infect Dis. 2019 Dec;19(12):e405-21.
https://pmc.ncbi.nlm.nih.gov/articles/PMC8559573
http://www.ncbi.nlm.nih.gov/pubmed/31699664?tool=bestpractice.com
Duration of therapy depends on clinical response and resolution of any immune defect; weeks to months of therapy are typically required. Consult an infectious disease specialist for further guidance on when to transition to oral therapy, or taper or stop therapy.[12]Cornely OA, Alastruey-Izquierdo A, Arenz D, et al. Global guideline for the diagnosis and management of mucormycosis: an initiative of the European Confederation of Medical Mycology in cooperation with the Mycoses Study Group Education and Research Consortium. Lancet Infect Dis. 2019 Dec;19(12):e405-21.
https://pmc.ncbi.nlm.nih.gov/articles/PMC8559573
http://www.ncbi.nlm.nih.gov/pubmed/31699664?tool=bestpractice.com
Antifungal therapy: treatment failure
Salvage antifungal therapy is recommended in patients with treatment failure (i.e., due to refractory mucormycosis or toxicity/intolerance to first-line regimens). The choice of drug for salvage therapy depends on the drug used initially. As only two drug classes are recommended for mucormycosis, salvage therapy typically involves switching to the other drug class.[12]Cornely OA, Alastruey-Izquierdo A, Arenz D, et al. Global guideline for the diagnosis and management of mucormycosis: an initiative of the European Confederation of Medical Mycology in cooperation with the Mycoses Study Group Education and Research Consortium. Lancet Infect Dis. 2019 Dec;19(12):e405-21.
https://pmc.ncbi.nlm.nih.gov/articles/PMC8559573
http://www.ncbi.nlm.nih.gov/pubmed/31699664?tool=bestpractice.com
Salvage therapy with isavuconazonium or posaconazole can be considered in patients who do not respond to, or experience toxicity with, initial treatment with amphotericin-B. Liposomal amphotericin-B, and amphotericin-B lipid complex, are suitable salvage options for cases of primary treatment failure with azole antifungals.[12]Cornely OA, Alastruey-Izquierdo A, Arenz D, et al. Global guideline for the diagnosis and management of mucormycosis: an initiative of the European Confederation of Medical Mycology in cooperation with the Mycoses Study Group Education and Research Consortium. Lancet Infect Dis. 2019 Dec;19(12):e405-21.
https://pmc.ncbi.nlm.nih.gov/articles/PMC8559573
http://www.ncbi.nlm.nih.gov/pubmed/31699664?tool=bestpractice.com
Combination antifungal therapy may be used as salvage therapy (and also as initial therapy in immunocompromised patients due to their poor prognosis).[61]Lu B, Ha D, Shen S, et al. Combination antifungal therapy for invasive mucormycosis in immunocompromised hosts: a single-center experience. Open Forum Infect Dis. 2024 Jun;11(6):ofae103.
https://pmc.ncbi.nlm.nih.gov/articles/PMC11181191
http://www.ncbi.nlm.nih.gov/pubmed/38887478?tool=bestpractice.com
[62]Smith C, Lee SC. Current treatments against mucormycosis and future directions. PLoS Pathog. 2022 Oct;18(10):e1010858.
https://pmc.ncbi.nlm.nih.gov/articles/PMC9560507
http://www.ncbi.nlm.nih.gov/pubmed/36227854?tool=bestpractice.com
Treatment guidelines only marginally recommend combination therapy, largely due to a lack of evidence demonstrating harm rather than evidence indicating clear benefit.[12]Cornely OA, Alastruey-Izquierdo A, Arenz D, et al. Global guideline for the diagnosis and management of mucormycosis: an initiative of the European Confederation of Medical Mycology in cooperation with the Mycoses Study Group Education and Research Consortium. Lancet Infect Dis. 2019 Dec;19(12):e405-21.
https://pmc.ncbi.nlm.nih.gov/articles/PMC8559573
http://www.ncbi.nlm.nih.gov/pubmed/31699664?tool=bestpractice.com
There is the potential for an increased risk of toxicity. Consult an infectious disease specialist for further guidance on using combination therapy.
Specific management of underlying medical problem
Patients with diabetes mellitus (rhino-orbito-cerebral disease is the most common)
Transplant recipients (solid organ/stem cell) (sinopulmonary disease is the most common)
Discontinuing or reducing immunosuppressive agents such as corticosteroids and chemotherapy whenever feasible is encouraged.[3]Spellberg B, Edwards J Jr, Ibrahim A. Novel perspectives on mucormycosis: pathophysiology, presentation, and management. Clin Microbiol Rev. 2005 Jul;18(3):556-69.
https://www.ncbi.nlm.nih.gov/pmc/articles/PMC1195964
http://www.ncbi.nlm.nih.gov/pubmed/16020690?tool=bestpractice.com
Giving granulocyte-colony stimulating factor (G-CSF), granulocyte macrophage-colony stimulating factor (GM-CSF), and interferon gamma may be beneficial by reversing therapy-induced neutropenia.[2]Steinbrink JM, Miceli MH. Mucormycosis. Infect Dis Clin North Am. 2021 Jun;35(2):435-52.
https://pmc.ncbi.nlm.nih.gov/articles/PMC10110349
http://www.ncbi.nlm.nih.gov/pubmed/34016285?tool=bestpractice.com
In hematology patients with mucormycosis and ongoing neutropenia, G-CSF has been used as an adjunct to antifungal therapy in several small patient cohorts.[12]Cornely OA, Alastruey-Izquierdo A, Arenz D, et al. Global guideline for the diagnosis and management of mucormycosis: an initiative of the European Confederation of Medical Mycology in cooperation with the Mycoses Study Group Education and Research Consortium. Lancet Infect Dis. 2019 Dec;19(12):e405-21.
https://pmc.ncbi.nlm.nih.gov/articles/PMC8559573
http://www.ncbi.nlm.nih.gov/pubmed/31699664?tool=bestpractice.com
Several case reports suggest that interferon gamma may be an effective treatment, including a case of abdominal mucormycosis unresponsive to conventional therapy that improved with nivolumab and interferon gamma.[63]Grimaldi D, Pradier O, Hotchkiss RS, et al. Nivolumab plus interferon-γ in the treatment of intractable mucormycosis. Lancet Infect Dis. 2017 Jan;17(1):18.
https://www.thelancet.com/journals/laninf/article/PIIS1473-3099(16)30541-2/fulltext
Interferon gamma was also successfully used in an immunocompetent patient with invasive cutaneous mucormycosis after severe burns, leading to rapid clinical improvement and immune recovery.[64]Tawfik DM, Dereux C, Tremblay JA, et al. Interferon gamma as an immune modulating adjunct therapy for invasive mucormycosis after severe burn - a case report. Front Immunol. 2022 Aug 22;13:883638.
https://pmc.ncbi.nlm.nih.gov/articles/PMC9442803
http://www.ncbi.nlm.nih.gov/pubmed/36072605?tool=bestpractice.com
However, adequate controlled trials are lacking.[3]Spellberg B, Edwards J Jr, Ibrahim A. Novel perspectives on mucormycosis: pathophysiology, presentation, and management. Clin Microbiol Rev. 2005 Jul;18(3):556-69.
https://www.ncbi.nlm.nih.gov/pmc/articles/PMC1195964
http://www.ncbi.nlm.nih.gov/pubmed/16020690?tool=bestpractice.com
Patients with iron overload
Avoiding use of deferoxamine as an iron chelator is recommended. Alternatives include suitable hydroxypyridinone iron chelators (e.g., deferiprone, deferasirox).[65]Ibrahim AS, Edwards JE Jr, Fu Y, et al. Deferiprone iron chelation as a novel therapy for experimental mucormycosis. J Antimicrob Chemother. 2006 Nov;58(5):1070-3.
http://jac.oxfordjournals.org/content/58/5/1070.long
http://www.ncbi.nlm.nih.gov/pubmed/16928702?tool=bestpractice.com