The main antiphospholipid syndrome (APS) treatment goals are managing acute thrombosis, preventing thrombosis recurrence, and reducing pregnancy morbidity.[8]Lim W, Crowther MA, Eikelboom JW. Management of antiphospholipid antibody syndrome: a systematic review. JAMA. 2006 Mar 1;295(9):1050-7.
http://jama.ama-assn.org/cgi/content/full/295/9/1050
http://www.ncbi.nlm.nih.gov/pubmed/16507806?tool=bestpractice.com
Patients should be instructed on the signs and symptoms of thrombosis so that they can identify potential events early and seek emergency evaluation.
Patients should also be evaluated and treated for other risk factors of thromboembolism (previous history of thromboembolism, obesity, smoking, diabetes, immobilisation, hypertension, hyperlipidaemia, and oestrogen use). This includes smoking cessation and management of hyperlipidaemia as appropriate.
Women should be advised regarding risks associated with pregnancy (i.e., personal risk of thromboembolism during pregnancy and the immediate postnatal period, as well as the risk of pregnancy loss and pregnancy morbidity).
Management of thrombosis
Once the diagnosis is confirmed, patients are initially anticoagulated with unfractionated heparin or low molecular weight heparin (LMWH), followed by oral anticoagulation with a vitamin K antagonist (e.g., warfarin), providing there are no contraindications to therapy with these agents.[8]Lim W, Crowther MA, Eikelboom JW. Management of antiphospholipid antibody syndrome: a systematic review. JAMA. 2006 Mar 1;295(9):1050-7.
http://jama.ama-assn.org/cgi/content/full/295/9/1050
http://www.ncbi.nlm.nih.gov/pubmed/16507806?tool=bestpractice.com
[43]Tektonidou MG, Andreoli L, Limper M, et al. EULAR recommendations for the management of antiphospholipid syndrome in adults. Ann Rheum Dis. 2019 Oct;78(10):1296-304.
https://ard.bmj.com/content/78/10/1296.long
http://www.ncbi.nlm.nih.gov/pubmed/31092409?tool=bestpractice.com
Patients with APS and an unprovoked venous thromboembolism have a high risk of recurrent thrombosis after cessation of anticoagulation, so the general recommendation is to continue anticoagulation long term.[8]Lim W, Crowther MA, Eikelboom JW. Management of antiphospholipid antibody syndrome: a systematic review. JAMA. 2006 Mar 1;295(9):1050-7.
http://jama.ama-assn.org/cgi/content/full/295/9/1050
http://www.ncbi.nlm.nih.gov/pubmed/16507806?tool=bestpractice.com
[43]Tektonidou MG, Andreoli L, Limper M, et al. EULAR recommendations for the management of antiphospholipid syndrome in adults. Ann Rheum Dis. 2019 Oct;78(10):1296-304.
https://ard.bmj.com/content/78/10/1296.long
http://www.ncbi.nlm.nih.gov/pubmed/31092409?tool=bestpractice.com
[44]Derksen RH, de Groot PG, Kater L, et al. Patients with antiphospholipid antibodies and venous thrombosis should receive long term anticoagulant treatment. Ann Rheum Dis. 1993 Sep;52(9):689-92.
http://www.ncbi.nlm.nih.gov/pmc/articles/PMC1005149/pdf/annrheumd00484-0071.pdf
http://www.ncbi.nlm.nih.gov/pubmed/8239766?tool=bestpractice.com
[45]Schulman S, Svenungsson E, Granqvist S. Anticardiolipin antibodies predict early recurrence of thromboembolism and death among patients with venous thromboembolism following anticoagulant therapy: Duration of Anticoagulation Study Group. Am J Med. 1998 Apr;104(4):332-8.
http://www.ncbi.nlm.nih.gov/pubmed/9576405?tool=bestpractice.com
Guidance for patients with APS with provoked thrombosis is less clear because there is lack of evidence with regard to duration of anticoagulation in patients with APS in this setting. Consideration should be given to the provoking factor associated with the thrombotic event and bleeding risks associated with long-term anticoagulation. Patients with a history of an unprovoked venous thromboembolic event should be anticoagulated with a vitamin K antagonist (e.g., warfarin) at a target international normalised ratio (INR) of 2.5 (range 2-3). Evidence suggests that high-intensity warfarin is no better than regular-intensity warfarin.[46]Crowther MA, Ginsberg JS, Julian J, et al. A comparison of two intensities of warfarin for the prevention of recurrent thrombosis in patients with the antiphospholipid antibody syndrome. N Engl J Med. 2003 Sep 18;349(12):1133-8.
http://www.nejm.org/doi/full/10.1056/NEJMoa035241#t=article
http://www.ncbi.nlm.nih.gov/pubmed/13679527?tool=bestpractice.com
[47]Finazzi G, Marchioli R, Brancaccio V, et al. A randomized clinical trial of high-intensity warfarin vs. conventional antithrombotic therapy for the prevention of recurrent thrombosis in patients with the antiphospholipid syndrome (WAPS). J Thromb Haemost. 2005 May;3(5):848-53.
http://onlinelibrary.wiley.com/doi/10.1111/j.1538-7836.2005.01340.x/full
http://www.ncbi.nlm.nih.gov/pubmed/15869575?tool=bestpractice.com
However, patients with recurrent venous thromboembolic events were excluded from these studies.
Management of other risk factors for thromboembolism is crucial. Smoking cessation and management of hyperlipidaemia, hypertension, diabetes, and obesity, as well as addressing factors of immobility and oestrogen must be aggressively managed.
Optimal treatment for patients with previous arterial events remains controversial due to the lack of good prospective studies in this group. High-intensity warfarin therapy (INR range 3-4) or addition of low-dose aspirin to anticoagulation have been advocated for management of these patients. However, existing data have not been able to prove that these approaches are superior over the standard INR goal range of 2-3.
Management of recurrent events in patients who are already anticoagulated at a higher therapeutic INR is particularly difficult. Patients with recurrent thrombosis should have a thorough review to understand the factors involved. Patients with recurrent thrombosis despite therapeutic anticoagulation may need a target INR of 3-4 and may benefit from antiplatelet therapies.[48]Okuma H, Kitagawa Y, Yasuda T, et al. Comparison between single antiplatelet therapy and combination of antiplatelet and anticoagulation therapy for secondary prevention in ischemic stroke patients with antiphospholipid syndrome. Int J Med Sci. 2009 Dec 5;7(1):15-18.
https://www.medsci.org/v07p0015.htm
http://www.ncbi.nlm.nih.gov/pubmed/20046230?tool=bestpractice.com
Chromogenic factor X or II testing with simultaneous INR testing can be considered under these circumstances to guide INR target ranges, or these tests can be used instead of the INR in circumstances where the lupus anticoagulant also affects the prothrombin time.[49]Cohen H, Efthymiou M, Devreese KMJ. Monitoring of anticoagulation in thrombotic antiphospholipid syndrome. J Thromb Haemost. 2021 Apr;19(4):892-908.
https://www.jthjournal.org/article/S1538-7836(22)00710-3/fulltext
http://www.ncbi.nlm.nih.gov/pubmed/33325604?tool=bestpractice.com
Direct oral anticoagulants are not recommended for APS.[50]Khairani CD, Bejjani A, Piazza G, et al. Direct oral anticoagulants vs vitamin K antagonists in patients with antiphospholipid syndromes: meta-analysis of randomized trials. J Am Coll Cardiol. 2023 Jan 3;81(1):16-30.
https://www.sciencedirect.com/science/article/pii/S073510972207098X
http://www.ncbi.nlm.nih.gov/pubmed/36328154?tool=bestpractice.com
The European Medicines Agency, the UK-based Medicines and Healthcare products Regulatory Agency, and the International Society of Haemostasis and Thrombosis do not recommend these drugs in patients with APS, particularly high-risk patients (i.e., those who test positive for all 3 antiphospholipid tests, have prior arterial thrombosis, small vessel thrombosis or organ involvement, or heart valve disease according to Sydney criteria). This is due to the associated increased rates of recurrent thrombotic events compared with warfarin.[51]Medicines and Healthcare products Regulatory Agency. Direct-acting oral anticoagulants (DOACs): increased risk of recurrent thrombotic events in patients with antiphospholipid syndrome. June 2019 [internet publication].
https://www.gov.uk/drug-safety-update/direct-acting-oral-anticoagulants-doacs-increased-risk-of-recurrent-thrombotic-events-in-patients-with-antiphospholipid-syndrome
One randomised trial comparing rivaroxaban and warfarin (TRAPS trial) among patients with APS and at risk of thromboembolic events or with a history of thrombosis was terminated early due to a high number of thromboembolic events in the rivaroxaban arm (none were reported in the warfarin arm).[52]Pengo V, Denas G, Zoppellaro G, et al. Rivaroxaban vs warfarin in high-risk patients with antiphospholipid syndrome. Blood. 2018 Sep 27;132(13):1365-71.
https://ashpublications.org/blood/article/132/13/1365/105711
http://www.ncbi.nlm.nih.gov/pubmed/30002145?tool=bestpractice.com
In a randomised controlled trial comparing apixaban with warfarin (ASTRO-APS) in patients with thrombotic APS, there was a higher rate of thrombosis (particularly stroke) in the group receiving apixaban.[53]Woller SC, Stevens SM, Kaplan D, et al. Apixaban compared with warfarin to prevent thrombosis in thrombotic antiphospholipid syndrome: a randomized trial. Blood Adv. 2022 Mar 22;6(6):1661-70.
https://ashpublications.org/bloodadvances/article/6/6/1661/477384/Apixaban-compared-with-warfarin-to-prevent
http://www.ncbi.nlm.nih.gov/pubmed/34662890?tool=bestpractice.com
Management of pregnancy
Management of pregnancy in women with APS encompasses both prevention of maternal thrombotic complications and prevention of pregnancy morbidity. Pregnancies of women with APS should ideally be managed by experienced multidisciplinary teams, including a haematologist, a rheumatologist, and an obstetrician.
Women who take warfarin should switch to anticoagulation with low-dose aspirin and heparin as soon as pregnancy is confirmed, ideally before week 6 of gestation, because of the teratogenic effects of warfarin.[43]Tektonidou MG, Andreoli L, Limper M, et al. EULAR recommendations for the management of antiphospholipid syndrome in adults. Ann Rheum Dis. 2019 Oct;78(10):1296-304.
https://ard.bmj.com/content/78/10/1296.long
http://www.ncbi.nlm.nih.gov/pubmed/31092409?tool=bestpractice.com
Women with obstetric APS and no thrombotic history should receive prophylactic low-dose aspirin with prophylactic LMWH, during pregnancy and the postnatal period (6-8 weeks).[43]Tektonidou MG, Andreoli L, Limper M, et al. EULAR recommendations for the management of antiphospholipid syndrome in adults. Ann Rheum Dis. 2019 Oct;78(10):1296-304.
https://ard.bmj.com/content/78/10/1296.long
http://www.ncbi.nlm.nih.gov/pubmed/31092409?tool=bestpractice.com
[54]Hamulyák EN, Scheres LJ, Marijnen MC, et al. Aspirin or heparin or both for improving pregnancy outcomes in women with persistent antiphospholipid antibodies and recurrent pregnancy loss. Cochrane Database Syst Rev. 2020 May 2;5:CD012852.
https://www.cochranelibrary.com/cdsr/doi/10.1002/14651858.CD012852.pub2/full
http://www.ncbi.nlm.nih.gov/pubmed/32358837?tool=bestpractice.com
[55]Sammaritano LR, Bermas BL, Chakravarty EE, et al. 2020 American College of Rheumatology guideline for the management of reproductive health in rheumatic and musculoskeletal diseases. Arthritis Rheumatol. 2020 Apr;72(4):529-56.
https://onlinelibrary.wiley.com/doi/10.1002/art.41191
http://www.ncbi.nlm.nih.gov/pubmed/32090480?tool=bestpractice.com
[
]
For women with persistent antiphospholipid antibodies and recurrent pregnancy loss, how does heparin plus aspirin compare with aspirin alone?/cca.html?targetUrl=https://www.cochranelibrary.com/cca/doi/10.1002/cca.3212/fullShow me the answer
Women with APS and a previous history of thrombosis should receive anticoagulation throughout pregnancy and the postnatal period (6-8 weeks).[43]Tektonidou MG, Andreoli L, Limper M, et al. EULAR recommendations for the management of antiphospholipid syndrome in adults. Ann Rheum Dis. 2019 Oct;78(10):1296-304.
https://ard.bmj.com/content/78/10/1296.long
http://www.ncbi.nlm.nih.gov/pubmed/31092409?tool=bestpractice.com
[56]Royal College of Obstetricians and Gynaecologists. Reducing the risk of thrombosis and embolism during pregnancy and the puerperium. Green-top Guideline No. 37a. Apr 2015. [internet publication].
https://www.rcog.org.uk/globalassets/documents/guidelines/gtg-37a.pdf
Frequent antenatal examinations and serial ultrasonography are recommended, owing to the risk of adverse pregnancy outcomes (pre-eclampsia, intrauterine growth restriction, and placental abruption).
[56]Royal College of Obstetricians and Gynaecologists. Reducing the risk of thrombosis and embolism during pregnancy and the puerperium. Green-top Guideline No. 37a. Apr 2015. [internet publication].
https://www.rcog.org.uk/globalassets/documents/guidelines/gtg-37a.pdf
[57]American College of Obstetricians and Gynecologists. ACOG practice bulletin no. 132: antiphospholipid syndrome. Dec 2012 [internet publication].
https://www.acog.org/clinical/clinical-guidance/practice-bulletin/articles/2012/12/antiphospholipid-syndrome
Fetal monitoring should include uterine artery Doppler scanning at 20-24 weeks to check for evidence of increased vascular resistance, which has been shown to predict placental dysfunction in women with APS.[58]Hunt BJ, Missfelder-Lobos H, Parra-Cordero M, et al. Pregnancy outcome and fibrinolytic, endothelial and coagulation markers in women undergoing uterine artery Doppler screening at 23 weeks. J Thromb Haemost. 2009 Jun;7(6):955-61.
http://onlinelibrary.wiley.com/doi/10.1111/j.1538-7836.2009.03344.x/full
http://www.ncbi.nlm.nih.gov/pubmed/19320824?tool=bestpractice.com
If this is abnormal, serial growth scans should be performed to monitor for intrauterine growth restriction.
In the postnatal period, women who were previously been receiving warfarin may restart warfarin and discontinue heparin. It is safe for the neonate to breastfeed while the mother is taking either heparin or warfarin.
Management of antiphospholipid antibodies (incidental aPL)
Patients who have antiphospholipid antibodies (lupus anticoagulant, anticardiolipin antibody, and anti-beta2-glycoprotein I) but no thrombotic or related obstetric complications (i.e., do not fit criteria for APS) are considered to have incidental aPL. Such patients may be at increased risk of thrombosis, but it is not possible to identify which specific patients are at risk.[59]Erkan D, Lockshin MD; APS ACTION members. APS ACTION - AntiPhospholipid Syndrome Alliance for Clinical Trials and International Networking. Lupus. 2012 Jun;21(7):695-8.
http://lup.sagepub.com/content/21/7/695.long
http://www.ncbi.nlm.nih.gov/pubmed/22635205?tool=bestpractice.com
Thus, attention should be paid to management of risk factors for cardiovascular and venous thromboembolic disease in these patients.
Evidence is conflicting regarding the use of aspirin in patients with incidental aPL. Some retrospective studies suggest a protective effect against thrombosis, while a placebo-controlled trial showed no such benefit.[60]Hereng T, Lambert M, Hachulla E, et al. Influence of aspirin on the clinical outcomes of 103 anti-phospholipid antibodies-positive patients. Lupus. 2008 Jan;17(1):11-5.
http://www.ncbi.nlm.nih.gov/pubmed/18089677?tool=bestpractice.com
[61]Erkan D, Yazici Y, Peterson MG, et al. A cross-sectional study of clinical thrombotic risk factors and preventive treatments in antiphospholipid syndrome. Rheumatology (Oxford). 2002 Aug;41(8):924-9.
http://rheumatology.oxfordjournals.org/content/41/8/924.long
http://www.ncbi.nlm.nih.gov/pubmed/12154210?tool=bestpractice.com
[62]Erkan D, Harrison MJ, Levy R, et al. Aspirin for primary thrombosis prevention in the antiphospholipid syndrome: a randomized, double-blind, placebo-controlled trial in asymptomatic antiphospholipid antibody-positive individuals. Arthritis Rheum. 2007 Jul;56(7):2382-91.
http://onlinelibrary.wiley.com/doi/10.1002/art.22663/full
http://www.ncbi.nlm.nih.gov/pubmed/17599766?tool=bestpractice.com
Meta-analysis based on limited data concluded that patients with aPL who were treated with aspirin had a lower risk of thrombosis.[63]Arnaud L, Mathian A, Ruffatti A, et al. Efficacy of aspirin for the primary prevention of thrombosis in patients with antiphospholipid antibodies: an international and collaborative meta-analysis. Autoimmun Rev. 2014 Mar;13(3):281-91.
http://www.ncbi.nlm.nih.gov/pubmed/24189281?tool=bestpractice.com
European League Against Rheumatism guidelines recommend using aspirin in patients with incidental aPL, triple positive aPL or in patients with aPL associated with systemic lupus erythematosus.[43]Tektonidou MG, Andreoli L, Limper M, et al. EULAR recommendations for the management of antiphospholipid syndrome in adults. Ann Rheum Dis. 2019 Oct;78(10):1296-304.
https://ard.bmj.com/content/78/10/1296.long
http://www.ncbi.nlm.nih.gov/pubmed/31092409?tool=bestpractice.com
There are additional concerns regarding the use of aspirin; trials among healthy individuals have suggested that the benefit of reducing thrombosis is less than the bleeding risk, and, among individuals with diabetes, evidence suggests the use of aspirin is ineffective in reducing the risk of non-fatal myocardial infarction or cardiovascular death and may still increase the risk of major bleeding.[64]Christiansen M, Grove EL, Hvas AM. Primary prevention of cardiovascular events with aspirin: toward more harm than benefit-a systematic review and meta-analysis. Semin Thromb Hemost. 2019 Jul;45(5):478-89.
http://www.ncbi.nlm.nih.gov/pubmed/31096304?tool=bestpractice.com
During pregnancy, women with incidental aPL are usually given aspirin only, followed by 6 weeks postnatal thromboprophylaxis.[57]American College of Obstetricians and Gynecologists. ACOG practice bulletin no. 132: antiphospholipid syndrome. Dec 2012 [internet publication].
https://www.acog.org/clinical/clinical-guidance/practice-bulletin/articles/2012/12/antiphospholipid-syndrome
[65]Ziakas PD, Pavlou M, Voulgarelis M. Heparin treatment in antiphospholipid syndrome with recurrent pregnancy loss: a systematic review and meta-analysis. Obstet Gynecol. 2010 Jun;115(6):1256-62.
http://www.ncbi.nlm.nih.gov/pubmed/20502298?tool=bestpractice.com
Management of catastrophic APS
Catastrophic APS is a rare manifestation of APS. Patients present with multiorgan impairment due to widespread thromboses involving three or more organs/tissues.[19]Erkan D, Lockshin MD. New approaches for managing antiphospholipid syndrome. Nat Clin Pract Rheumatol. 2009 Mar;5(3):160-70.
http://www.ncbi.nlm.nih.gov/pubmed/19252521?tool=bestpractice.com
[66]Aguiar CL, Erkan D. Catastrophic antiphospholipid syndrome: how to diagnose a rare but highly fatal disease. Ther Adv Musculoskelet Dis. 2013 Dec;5(6):305-14.
http://www.ncbi.nlm.nih.gov/pmc/articles/PMC3836378
http://www.ncbi.nlm.nih.gov/pubmed/24294304?tool=bestpractice.com
Thrombosis is commonly microvascular thrombosis rather than large-vessel thrombosis. There is an associated high mortality (up to 50%).[67]Kazzaz NM, McCune WJ, Knight JS. Treatment of catastrophic antiphospholipid syndrome. Curr Opin Rheumatol. 2016 May;28(3):218-27.
https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4958413
http://www.ncbi.nlm.nih.gov/pubmed/26927441?tool=bestpractice.com
Patients require aggressive management with anticoagulation and consideration of adjunctive immunosuppressive therapy.[43]Tektonidou MG, Andreoli L, Limper M, et al. EULAR recommendations for the management of antiphospholipid syndrome in adults. Ann Rheum Dis. 2019 Oct;78(10):1296-304.
https://ard.bmj.com/content/78/10/1296.long
http://www.ncbi.nlm.nih.gov/pubmed/31092409?tool=bestpractice.com
[68]Erkan D. Expert perspective: management of microvascular and catastrophic antiphospholipid syndrome. Arthritis Rheumatol. 2021 Oct;73(10):1780-90.
http://www.ncbi.nlm.nih.gov/pubmed/34114366?tool=bestpractice.com
This may include corticosteroids, immunoglobulins, and/or plasma exchange.[19]Erkan D, Lockshin MD. New approaches for managing antiphospholipid syndrome. Nat Clin Pract Rheumatol. 2009 Mar;5(3):160-70.
http://www.ncbi.nlm.nih.gov/pubmed/19252521?tool=bestpractice.com
[43]Tektonidou MG, Andreoli L, Limper M, et al. EULAR recommendations for the management of antiphospholipid syndrome in adults. Ann Rheum Dis. 2019 Oct;78(10):1296-304.
https://ard.bmj.com/content/78/10/1296.long
http://www.ncbi.nlm.nih.gov/pubmed/31092409?tool=bestpractice.com
In refractory cases, some case reports suggest rituximab, eculizumab, or daratumumab may be of benefit.[43]Tektonidou MG, Andreoli L, Limper M, et al. EULAR recommendations for the management of antiphospholipid syndrome in adults. Ann Rheum Dis. 2019 Oct;78(10):1296-304.
https://ard.bmj.com/content/78/10/1296.long
http://www.ncbi.nlm.nih.gov/pubmed/31092409?tool=bestpractice.com
[69]Rubenstein E, Arkfeld DG, Metyas S, et al. Rituximab treatment for resistant antiphospholipid syndrome. J Rheumatol. 2006 Feb;33(2):355-7.
http://www.ncbi.nlm.nih.gov/pubmed/16465669?tool=bestpractice.com
[70]Tinti MG, Carnevale V, Inglese M, et al. Eculizumab in refractory catastrophic antiphospholipid syndrome: a case report and systematic review of the literature. Clin Exp Med. 2019 Aug;19(3):281-8.
http://www.ncbi.nlm.nih.gov/pubmed/31214910?tool=bestpractice.com
[71]Pleguezuelo DE, Díaz-Simón R, Cabrera-Marante O, et al. Case report: resetting the humoral immune response by targeting plasma cells with daratumumab in anti-phospholipid syndrome. Front Immunol. 2021;12:667515.
https://www.frontiersin.org/journals/immunology/articles/10.3389/fimmu.2021.667515/full
http://www.ncbi.nlm.nih.gov/pubmed/33912194?tool=bestpractice.com
A small, open-label trial of rituximab, a monoclonal antibody that targets the CD20 antigen, showed improvement in some manifestations, such as thrombocytopenia.[72]Erkan D, Vega J, Ramón G, et al. A pilot open-label phase II trial of rituximab for non-criteria manifestations of antiphospholipid syndrome. Arthritis Rheum. 2013 Feb;65(2):464-71.
https://onlinelibrary.wiley.com/doi/epdf/10.1002/art.37759
http://www.ncbi.nlm.nih.gov/pubmed/23124321?tool=bestpractice.com
Daratumumab, a monoclonal antibody that targets the CD38 antigen, is currently being studied in the DARE-APS trial.[73]ClinicalTrials.gov. Daratumumab in primary antiphospholipid syndrome (DARE-APS). ClinicalTrials.gov Identifier: NCT05671757. Jul 2024 [internet publication].
https://clinicaltrials.gov/study/NCT05671757