Treatment for MDS is guided by risk assessment, disease type/characteristics (e.g., cytogenetic abnormalities, ring sideroblasts), symptoms/severity of cytopenias, and erythropoietin levels (in patients with anaemia).[12]Killick SB, Ingram W, Culligan D, et al. British Society for Haematology guidelines for the management of adult myelodysplastic syndromes. Br J Haematol. 2021 Jul;194(2):267-81.
https://onlinelibrary.wiley.com/doi/10.1111/bjh.17612
http://www.ncbi.nlm.nih.gov/pubmed/34180045?tool=bestpractice.com
[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Other important treatment considerations include patient age, performance status, comorbidities, and patient preference/goals.
Risk assessment informs treatment. The revised International Prognostic Scoring System (IPSS-R) is used to determine whether patients have lower-risk disease or higher-risk disease. See Criteria.
All patients should be encouraged to enrol in a clinical trial (if available and eligible), particularly those with higher-risk disease and those unresponsive to treatment.[12]Killick SB, Ingram W, Culligan D, et al. British Society for Haematology guidelines for the management of adult myelodysplastic syndromes. Br J Haematol. 2021 Jul;194(2):267-81.
https://onlinelibrary.wiley.com/doi/10.1111/bjh.17612
http://www.ncbi.nlm.nih.gov/pubmed/34180045?tool=bestpractice.com
[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Supportive care
Supportive care is central to management of MDS. All symptomatic patients (lower- or higher-risk) should receive supportive care as appropriate, which includes: red blood cell (RBC) transfusions with iron chelation support (for anaemia); platelet transfusions (for thrombocytopenia and bleeding); and anti-infective therapy (e.g., antibiotics).[12]Killick SB, Ingram W, Culligan D, et al. British Society for Haematology guidelines for the management of adult myelodysplastic syndromes. Br J Haematol. 2021 Jul;194(2):267-81.
https://onlinelibrary.wiley.com/doi/10.1111/bjh.17612
http://www.ncbi.nlm.nih.gov/pubmed/34180045?tool=bestpractice.com
[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Transfusions
RBC transfusion (with iron chelation therapy support if needed) is recommended for symptomatic anaemia.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Patients should be transfused with the minimum number of units necessary to relieve symptoms of anaemia or to return the patient to a safe haemoglobin level.
RBC transfusions are usually warranted if haemoglobin falls below 7 g/dL or 8 g/dL.[12]Killick SB, Ingram W, Culligan D, et al. British Society for Haematology guidelines for the management of adult myelodysplastic syndromes. Br J Haematol. 2021 Jul;194(2):267-81.
https://onlinelibrary.wiley.com/doi/10.1111/bjh.17612
http://www.ncbi.nlm.nih.gov/pubmed/34180045?tool=bestpractice.com
[67]Mo A, McQuilten ZK, Wood EM, et al. Red cell transfusion thresholds in myelodysplastic syndromes: a clinician survey to inform future clinical trials. Intern Med J. 2017 Jun;47(6):695-8.
http://www.ncbi.nlm.nih.gov/pubmed/28580745?tool=bestpractice.com
However, RBC transfusions should be individualised because symptomatic anaemia may occur at higher haemoglobin levels.
Platelet transfusions are recommended for thrombocytopenic bleeding.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Platelet transfusions should not be used routinely in patients with thrombocytopenia in the absence of bleeding unless platelet count is <10,000/microlitre.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Avoiding unnecessary platelet transfusions can improve quality of life and may reduce the risk of repeated suboptimal response to transfusion (platelet refractoriness).
All transfused blood products should be irradiated before use in patients who are potential candidates for allogeneic stem cell transplantation (SCT).[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Anti-infective therapy
Antibiotics are recommended for bacterial infections and prophylaxis may be considered when starting patients on therapy; consult local guidance.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Patients who have undergone allogeneic SCT should receive antibiotic prophylaxis alongside post-transplant immunosuppressive regimens used to manage graft-versus-host disease.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Allogeneic stem cell transplantation (SCT)
Allogeneic SCT is the only potentially curative therapy for MDS.[68]DeFilipp Z, Ciurea SO, Cutler C, et al. Hematopoietic cell transplantation in the management of myelodysplastic syndrome: an evidence-based review from the American Society for Transplantation and Cellular Therapy Committee on Practice Guidelines. Transplant Cell Ther. 2023 Feb;29(2):71-81.
https://www.sciencedirect.com/science/article/pii/S2666636722017821?via%3Dihub
http://www.ncbi.nlm.nih.gov/pubmed/36436780?tool=bestpractice.com
Allogeneic SCT is recommended for patients with high-risk disease, if eligible.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
It may be considered for select patients with lower-risk disease (e.g., intermediate risk according to IPSS-R with severe cytopenias; see Criteria).
Patients should be assessed for suitability for allogeneic SCT and referred for transplant evaluation as early as possible following diagnosis.[12]Killick SB, Ingram W, Culligan D, et al. British Society for Haematology guidelines for the management of adult myelodysplastic syndromes. Br J Haematol. 2021 Jul;194(2):267-81.
https://onlinelibrary.wiley.com/doi/10.1111/bjh.17612
http://www.ncbi.nlm.nih.gov/pubmed/34180045?tool=bestpractice.com
[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
[68]DeFilipp Z, Ciurea SO, Cutler C, et al. Hematopoietic cell transplantation in the management of myelodysplastic syndrome: an evidence-based review from the American Society for Transplantation and Cellular Therapy Committee on Practice Guidelines. Transplant Cell Ther. 2023 Feb;29(2):71-81.
https://www.sciencedirect.com/science/article/pii/S2666636722017821?via%3Dihub
http://www.ncbi.nlm.nih.gov/pubmed/36436780?tool=bestpractice.com
Many patients are unsuitable for allogeneic SCT because of advanced age, lack of a compatible donor (although becoming less common with use of haploidentical transplant), poor performance status, or comorbidities.
A matched sibling donor, unrelated donor, haploidentical donor, or cord blood donor can be used for allogeneic SCT.[68]DeFilipp Z, Ciurea SO, Cutler C, et al. Hematopoietic cell transplantation in the management of myelodysplastic syndrome: an evidence-based review from the American Society for Transplantation and Cellular Therapy Committee on Practice Guidelines. Transplant Cell Ther. 2023 Feb;29(2):71-81.
https://www.sciencedirect.com/science/article/pii/S2666636722017821?via%3Dihub
http://www.ncbi.nlm.nih.gov/pubmed/36436780?tool=bestpractice.com
Standard or reduced-intensity conditioning regimens may be considered.[68]DeFilipp Z, Ciurea SO, Cutler C, et al. Hematopoietic cell transplantation in the management of myelodysplastic syndrome: an evidence-based review from the American Society for Transplantation and Cellular Therapy Committee on Practice Guidelines. Transplant Cell Ther. 2023 Feb;29(2):71-81.
https://www.sciencedirect.com/science/article/pii/S2666636722017821?via%3Dihub
http://www.ncbi.nlm.nih.gov/pubmed/36436780?tool=bestpractice.com
Lower-risk disease: asymptomatic
Lower-risk disease (e.g., very-low, low, or intermediate risk according to IPSS-R) is associated with a relatively low risk of progression to acute myeloid leukaemia (AML) or death.
Treatment for lower-risk disease is focused on improving quality of life by reducing symptoms, reducing transfusion need, and preventing complications associated with cytopenias.
Patients with lower-risk disease who are asymptomatic can be monitored without treatment until symptoms, complications of cytopenias, or disease progression occur, or are likely to occur.[16]Fenaux P, Haase D, Santini V, et al; ESMO Guidelines Committee. Myelodysplastic syndromes: ESMO clinical practice guidelines for diagnosis, treatment and follow-up. Ann Oncol. 2021 Feb;32(2):142-56.
https://www.annalsofoncology.org/article/S0923-7534(20)43129-1/fulltext
http://www.ncbi.nlm.nih.gov/pubmed/33221366?tool=bestpractice.com
Lower-risk disease: symptomatic anaemia
For treatment of symptomatic anaemia in lower-risk patients, the National Comprehensive Cancer Network (NCCN) recommends stratifying patients based on erythropoietin levels and the following disease type/characteristics:[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
MDS-5q, i.e., MDS with del(5q), with or without one other cytogenetic abnormality except those involving chromosome 7
MDS-SF3B1, i.e., MDS with no del(5q), with or without other cytogenetic abnormalities, with ring sideroblasts ≥15% (or ≥5% with an SF3B1 mutation)
MDS with no del(5q), with or without other cytogenetic abnormalities, with ring sideroblasts <15% (or <5% with an SF3B1 mutation). See Classification.
MDS-5q with erythropoietin levels ≤500 IU/L
Lenalidomide (preferred) or an erythropoiesis-stimulating agent (ESA; e.g., epoetin alfa, darbepoetin alfa) is recommended for initial treatment of symptomatic anaemia in lower-risk patients with MDS-5q and erythropoietin levels ≤500 IU/L.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Patients who fail to respond (i.e., no improvement in haemoglobin or no reduction in RBC transfusion requirement) to an ESA prescribed first-line can be considered for lenalidomide therapy, if absolute neutrophil count is >500/microlitre and platelet count is >50,000/microlitre.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
If there is no response to initial treatment with lenalidomide or an ESA, a clinical trial or treatment with a hypomethylating agent (azacitidine [preferred]; decitabine; or decitabine/cedazuridine) is recommended.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
If there is no response to (or there is intolerance of) treatment with hypomethylating agents, patients can be treated with ivosidenib if they have IDH1 mutations, or considered for a clinical trial or allogeneic SCT if they do not have IDH1 mutations.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
MDS-5q with erythropoietin levels >500 IU/L
Lenalidomide is recommended for initial treatment of symptomatic anaemia in lower-risk patients with MDS-5q and erythropoietin levels >500 IU/L.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Patients with erythropoietin levels >500 IU/L are unlikely to benefit from treatment with ESAs.[69]Bohlius J, Bohlke K, Castelli R, et al. Management of cancer-associated anemia with erythropoiesis-stimulating agents: ASCO/ASH clinical practice guideline update. J Clin Oncol. 2019 May 20;37(15):1336-51.
http://www.ncbi.nlm.nih.gov/pubmed/30969847?tool=bestpractice.com
If there is no response to initial treatment, a clinical trial or treatment with a hypomethylating agent is recommended.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
If there is no response to (or there is intolerance of) treatment with hypomethylating agents, these patients can be treated with ivosidenib if they have IDH1 mutations, or considered for a clinical trial or allogeneic SCT if they do not have IDH1 mutations.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
MDS-SF3B1 with erythropoietin levels ≤500 IU/L
Luspatercept is recommended for initial treatment of symptomatic anaemia in lower-risk patients with MDS-SF3B1 and erythropoietin levels ≤500 IU/L.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
[70]Fenaux P, Platzbecker U, Mufti GJ, et al. Luspatercept in patients with lower-risk myelodysplastic syndromes. N Engl J Med. 2020 Jan 9;382(2):140-51.
https://www.nejm.org/doi/10.1056/NEJMoa1908892
http://www.ncbi.nlm.nih.gov/pubmed/31914241?tool=bestpractice.com
If there is no response to initial treatment, imetelstat or an ESA is recommended.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Granulocyte colony-stimulating factor (G-CSF; e.g., filgrastim) may be combined with an ESA to treat anaemia. Evidence suggests that G-CSF may improve the erythroid response rate of ESAs.[71]Hellström-Lindberg E, Negrin R, Stein R, et al. Erythroid response to treatment with G-CSF plus erythropoietin for the anaemia of patients with myelodysplastic syndromes: proposal for a predictive model. Br J Haematol. 1997 Nov;99(2):344-51.
http://www.ncbi.nlm.nih.gov/pubmed/9375752?tool=bestpractice.com
A validated decision model has been developed for predicting erythroid responses to ESAs plus G-CSF based on erythropoietin level and number of previous RBC transfusions.[72]Hellström-Lindberg E, Gulbrandsen N, Lindberg G, et al. A validated decision model for treating the anaemia of myelodysplastic syndromes with erythropoietin + granulocyte colony-stimulating factor: significant effects on quality of life. Br J Haematol. 2003 Mar;120(6):1037-46.
http://www.ncbi.nlm.nih.gov/pubmed/12648074?tool=bestpractice.com
If there is no response to treatment with imetelstat or ESAs (with or without G-CSF), patients can be considered for a clinical trial (if available and eligible) or treatment with a hypomethylating agent.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Patients who do not respond to (or are intolerant of) treatment with hypomethylating agents can be treated with ivosidenib if they have IDH1 mutations, or considered for a clinical trial or allogeneic SCT if they do not have IDH1 mutations.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Patients who do not respond to ivosidenib can be considered for a clinical trial or allogeneic SCT.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
MDS-SF3B1 with erythropoietin levels >500 IU/L
Luspatercept or imetelstat is recommended for initial treatment of symptomatic anaemia in lower-risk patients with MDS-SF3B1 and erythropoietin levels >500 IU/L.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
[70]Fenaux P, Platzbecker U, Mufti GJ, et al. Luspatercept in patients with lower-risk myelodysplastic syndromes. N Engl J Med. 2020 Jan 9;382(2):140-51.
https://www.nejm.org/doi/10.1056/NEJMoa1908892
http://www.ncbi.nlm.nih.gov/pubmed/31914241?tool=bestpractice.com
Lenalidomide can be considered if there is no response to initial treatment with luspatercept or imetelstat.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
If there is no response to treatment with lenalidomide, patients should be considered for a clinical trial or treatment with a hypomethylating agent.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Patients who do not respond to (or are intolerant of) treatment with hypomethylating agents can be treated with ivosidenib if they have IDH1 mutations, or considered for a clinical trial or allogeneic SCT if they do not have IDH1 mutations.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Patients who do not respond to ivosidenib can be considered for a clinical trial or allogeneic SCT.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
MDS with no del(5q) with ring sideroblasts <15% with erythropoietin levels ≤500 IU/L
An ESA alone or luspatercept is recommended for initial treatment of symptomatic anaemia in lower-risk patients with no del(5q) and ring sideroblasts <15% (or <5% with an SF3B1 mutation) and erythropoietin levels ≤500 IU/L.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
[73]Platzbecker U, Della Porta MG, Santini V, et al. Efficacy and safety of luspatercept versus epoetin alfa in erythropoiesis-stimulating agent-naive, transfusion-dependent, lower-risk myelodysplastic syndromes (COMMANDS): interim analysis of a phase 3, open-label, randomised controlled trial. Lancet. 2023 Jul 29;402(10399):373-85.
http://www.ncbi.nlm.nih.gov/pubmed/37311468?tool=bestpractice.com
Patients who fail to respond (i.e., no improvement in haemoglobin or no reduction in RBC transfusion requirement) to an ESA prescribed first-line can be considered for luspatercept therapy.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
G-CSF or lenalidomide may be combined with an ESA if there is no response to initial treatment with an ESA alone or luspatercept.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
[71]Hellström-Lindberg E, Negrin R, Stein R, et al. Erythroid response to treatment with G-CSF plus erythropoietin for the anaemia of patients with myelodysplastic syndromes: proposal for a predictive model. Br J Haematol. 1997 Nov;99(2):344-51.
http://www.ncbi.nlm.nih.gov/pubmed/9375752?tool=bestpractice.com
[72]Hellström-Lindberg E, Gulbrandsen N, Lindberg G, et al. A validated decision model for treating the anaemia of myelodysplastic syndromes with erythropoietin + granulocyte colony-stimulating factor: significant effects on quality of life. Br J Haematol. 2003 Mar;120(6):1037-46.
http://www.ncbi.nlm.nih.gov/pubmed/12648074?tool=bestpractice.com
Imetelstat or lenalidomide alone can also be considered if there is no response to initial treatment in these patients.
Patients who do not respond to treatment with an ESA (with or without G-CSF or lenalidomide) or imetelstat can be considered for a clinical trial or treatment with a hypomethylating agent.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
If there is no response to (or there is intolerance of) treatment with hypomethylating agents, patients can be treated with ivosidenib if they have IDH1 mutations, or considered for a clinical trial or allogeneic SCT if they do not have IDH1 mutations.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Patients who do not respond to ivosidenib can be considered for a clinical trial or allogeneic SCT.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
MDS with no del(5q) with ring sideroblasts <15% with erythropoietin levels >500 IU/L
Patients with MDS who have no del(5q) and ring sideroblasts <15% (or <5% with an SF3B1 mutation) and erythropoietin levels >500 IU/L should be evaluated for suitability for immunosuppressive therapy (IST). Patients who are likely to respond to IST (e.g., those with hypocellular bone marrow) can be treated with IST comprising antithymocyte globulin (ATG) with or without ciclosporin.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
[74]Stahl M, DeVeaux M, de Witte T, et al. The use of immunosuppressive therapy in MDS: clinical outcomes and their predictors in a large international patient cohort. Blood Adv. 2018 Jul;2(14):1765-72.
https://www.doi.org/10.1182/bloodadvances.2018019414
http://www.ncbi.nlm.nih.gov/pubmed/30037803?tool=bestpractice.com
Eltrombopag may be combined with IST. A corticosteroid should be given alongside ATG to prevent serum sickness.
IST may be effective in patients aged ≤60 years with ≤5% marrow blasts, or in those who have the following features: HLA-DR15 positivity; paroxysmal nocturnal haemoglobinuria (PNH) clone; or STAT-3 mutant T-cell clone. However, the evidence is mixed.[74]Stahl M, DeVeaux M, de Witte T, et al. The use of immunosuppressive therapy in MDS: clinical outcomes and their predictors in a large international patient cohort. Blood Adv. 2018 Jul;2(14):1765-72.
https://www.doi.org/10.1182/bloodadvances.2018019414
http://www.ncbi.nlm.nih.gov/pubmed/30037803?tool=bestpractice.com
[75]Sloand EM, Wu CO, Greenberg P, et al. Factors affecting response and survival in patients with myelodysplasia treated with immunosuppressive therapy. J Clin Oncol. 2008 May;26(15):2505-11.
https://www.doi.org/10.1200/JCO.2007.11.9214
http://www.ncbi.nlm.nih.gov/pubmed/18413642?tool=bestpractice.com
[76]Saunthararajah Y, Nakamura R, Wesley R, et al. A simple method to predict response to immunosuppressive therapy in patients with myelodysplastic syndrome. Blood. 2003 Oct;102(8):3025-7.
https://www.doi.org/10.1182/blood-2002-11-3325
http://www.ncbi.nlm.nih.gov/pubmed/12829603?tool=bestpractice.com
[77]Parikh AR, Olnes MJ, Barrett AJ. Immunomodulatory treatment of myelodysplastic syndromes: antithymocyte globulin, cyclosporine, and alemtuzumab. Semin Hematol. 2012 Oct;49(4):304-11.
https://www.doi.org/10.1053/j.seminhematol.2012.07.004
http://www.ncbi.nlm.nih.gov/pubmed/23079060?tool=bestpractice.com
[78]Saunthararajah Y, Nakamura R, Nam JM, et al. HLA-DR15 (DR2) is overrepresented in myelodysplastic syndrome and aplastic anemia and predicts a response to immunosuppression in myelodysplastic syndrome. Blood. 2002 Sep 1;100(5):1570-4.
https://www.sciencedirect.com/science/article/pii/S0006497120592367?via%3Dihub
http://www.ncbi.nlm.nih.gov/pubmed/12176872?tool=bestpractice.com
Patients who are unlikely to respond to IST, or who are unresponsive to initial treatment with IST, can be considered for a clinical trial, or treatment with a hypomethylating agent or imetelstat.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
[74]Stahl M, DeVeaux M, de Witte T, et al. The use of immunosuppressive therapy in MDS: clinical outcomes and their predictors in a large international patient cohort. Blood Adv. 2018 Jul;2(14):1765-72.
https://www.doi.org/10.1182/bloodadvances.2018019414
http://www.ncbi.nlm.nih.gov/pubmed/30037803?tool=bestpractice.com
Lenalidomide may also be considered if absolute neutrophil count is >500/microlitre and platelet count is >50,000/microlitre.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
If there is no response to (or there is intolerance of) treatment with hypomethylating agents, imetelstat, or lenalidomide, patients can be treated with ivosidenib if they have IDH1 mutations, or considered for a clinical trial or allogeneic SCT if they do not have IDH1 mutations.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Lower-risk disease: clinically relevant thrombocytopenia or neutropenia (without symptomatic anaemia)
A clinical trial or a hypomethylating agent is recommended for initial treatment of patients with lower-risk disease who have clinically relevant thrombocytopenia or neutropenia (without symptomatic anaemia).[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Patients likely to respond to IST (e.g., those with hypocellular bone marrow) can be considered for initial treatment with ATG plus ciclosporin (with or without eltrombopag).[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
[74]Stahl M, DeVeaux M, de Witte T, et al. The use of immunosuppressive therapy in MDS: clinical outcomes and their predictors in a large international patient cohort. Blood Adv. 2018 Jul;2(14):1765-72.
https://www.doi.org/10.1182/bloodadvances.2018019414
http://www.ncbi.nlm.nih.gov/pubmed/30037803?tool=bestpractice.com
Eltrombopag alone can be considered for treatment of severe or life-threatening thrombocytopenia in lower-risk patients.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
A hypomethylating agent (if not previously used) or ivosidenib (if patients have IDH1 mutations) can be considered if there is disease progression or no response to initial treatment of clinically relevant thrombocytopenia or neutropenia in lower-risk patients.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Romiplostim can be considered for treatment of severe or refractory thrombocytopenia.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
[79]Oliva EN, Alati C, Santini V, et al. Eltrombopag versus placebo for low-risk myelodysplastic syndromes with thrombocytopenia (EQoL-MDS): phase 1 results of a single-blind, randomised, controlled, phase 2 superiority trial. Lancet Haematol. 2017 Mar;4(3):e127-36.
http://www.ncbi.nlm.nih.gov/pubmed/28162984?tool=bestpractice.com
Patients who do not have IDH1 mutations should be considered for a clinical trial or allogeneic SCT.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Higher-risk disease
Patients with higher-risk disease (e.g., intermediate, high, or very high risk according to IPSS-R) have a poor prognosis (relatively increased risk of progression to AML or death).[12]Killick SB, Ingram W, Culligan D, et al. British Society for Haematology guidelines for the management of adult myelodysplastic syndromes. Br J Haematol. 2021 Jul;194(2):267-81.
https://onlinelibrary.wiley.com/doi/10.1111/bjh.17612
http://www.ncbi.nlm.nih.gov/pubmed/34180045?tool=bestpractice.com
[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Treatment for higher-risk disease is focused on delaying progression and prolonging survival, reducing symptoms and complications, and improving quality of life.
Higher-risk patients should be promptly referred for allogeneic SCT evaluation.[12]Killick SB, Ingram W, Culligan D, et al. British Society for Haematology guidelines for the management of adult myelodysplastic syndromes. Br J Haematol. 2021 Jul;194(2):267-81.
https://onlinelibrary.wiley.com/doi/10.1111/bjh.17612
http://www.ncbi.nlm.nih.gov/pubmed/34180045?tool=bestpractice.com
[80]Cutler CS, Lee SJ, Greenberg P, et al. A decision analysis of allogeneic bone marrow transplantation for the myelodysplastic syndromes: delayed transplantation for low-risk myelodysplasia is associated with improved outcome. Blood. 2004 Jul 15;104(2):579-85.
http://www.ncbi.nlm.nih.gov/pubmed/15039286?tool=bestpractice.com
[81]Oliansky DM, Antin JH, Bennett JM, et al. The role of cytotoxic therapy with hematopoietic stem cell transplantation in the therapy of myelodysplastic syndromes: an evidence-based review. Biol Blood Marrow Transplant. 2009 Feb;15(2):137-72.
http://www.ncbi.nlm.nih.gov/pubmed/19167676?tool=bestpractice.com
Patients should be encouraged to enrol in a clinical trial (if available and eligible), especially if they have poor prognostic markers (e.g., TP53 mutations).
Higher-risk disease: transplant candidate
Higher-risk patients may undergo immediate allogeneic SCT if suitable (e.g., based on age, performance status, comorbidities, patient preference, and donor availability).[12]Killick SB, Ingram W, Culligan D, et al. British Society for Haematology guidelines for the management of adult myelodysplastic syndromes. Br J Haematol. 2021 Jul;194(2):267-81.
https://onlinelibrary.wiley.com/doi/10.1111/bjh.17612
http://www.ncbi.nlm.nih.gov/pubmed/34180045?tool=bestpractice.com
[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Pre-transplant cytoreduction (debulking) using chemotherapy or hypomethylating agents is recommended to reduce marrow blasts to <5% in patients with high tumour burden.[12]Killick SB, Ingram W, Culligan D, et al. British Society for Haematology guidelines for the management of adult myelodysplastic syndromes. Br J Haematol. 2021 Jul;194(2):267-81.
https://onlinelibrary.wiley.com/doi/10.1111/bjh.17612
http://www.ncbi.nlm.nih.gov/pubmed/34180045?tool=bestpractice.com
[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
[53]de Witte T, Bowen D, Robin M, et al. Allogeneic hematopoietic stem cell transplantation for MDS and CMML: recommendations from an international expert panel. Blood. 2017 Mar 30;129(13):1753-62.
https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5524528
http://www.ncbi.nlm.nih.gov/pubmed/28096091?tool=bestpractice.com
Ivosidenib can be used for cytoreduction if there is no response to chemotherapy or hypomethylating agents, and the patient has IDH1 mutations.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
Cytoreduction may reduce the risk of post-transplant relapse. However, this has not yet been confirmed by prospective clinical trials.
Higher-risk disease: non-transplant candidate
Higher-risk patients who are unsuitable for allogeneic SCT can be considered for a clinical trial or initial treatment with a hypomethylating agent.[12]Killick SB, Ingram W, Culligan D, et al. British Society for Haematology guidelines for the management of adult myelodysplastic syndromes. Br J Haematol. 2021 Jul;194(2):267-81.
https://onlinelibrary.wiley.com/doi/10.1111/bjh.17612
http://www.ncbi.nlm.nih.gov/pubmed/34180045?tool=bestpractice.com
[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1
[82]Fenaux P, Giagounidis A, Selleslag D, et al. A randomized phase 3 study of lenalidomide versus placebo in RBC transfusion-dependent patients with Low-/Intermediate-1-risk myelodysplastic syndromes with del5q. Blood. 2011 Oct 6;118(14):3765-76.
http://www.ncbi.nlm.nih.gov/pubmed/21753188?tool=bestpractice.com
Azacitidine improves overall survival in higher-risk patients compared with supportive care and chemotherapy.[83]Fenaux P, Mufti GJ, Hellstrom-Lindberg E, et al. Efficacy of azacitidine compared with that of conventional care regimens in the treatment of higher-risk myelodysplastic syndromes: a randomised, open-label, phase III study. Lancet Oncol. 2009 Mar;10(3):223-32.
https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4086808
http://www.ncbi.nlm.nih.gov/pubmed/19230772?tool=bestpractice.com
A survival benefit with decitabine has not been shown in phase 3 trials, but a US-based registry study suggested similar survival to azacitidine.[84]Zeidan AM, Davidoff AJ, Long JB, et al. Comparative clinical effectiveness of azacitidine versus decitabine in older patients with myelodysplastic syndromes. Br J Haematol. 2016 Dec;175(5):829-40.
https://www.doi.org/10.1111/bjh.14305
http://www.ncbi.nlm.nih.gov/pubmed/27650975?tool=bestpractice.com
Oral decitabine/cedazuridine may be used instead of intravenous decitabine based on patient preference and convenience. In patients with higher-risk disease, treatment with a hypomethylating agent should continue until the patient stops responding or treatment becomes intolerable.
Patients who do not respond to initial treatment with a hypomethylating agent can be treated with ivosidenib if they have IDH1 mutations, or considered for a clinical trial if they do not have IDH1 mutations.[15]National Comprehensive Cancer Network. NCCN clinical practice guidelines in oncology: myelodysplastic syndromes [internet publication].
https://www.nccn.org/guidelines/category_1