Shiga toxin-producing Escherichia coli (STEC) HUS
Children with the typical presentation of bloody diarrhoea, abdominal pain, nausea, and vomiting should be hospitalised. This can expedite evaluation, and maintenance of intravascular volume, and thus possibly decrease the risk of complications and the risk of transmission.[8]Bell BP, Goldoft M, Griffin PM, et al. A multistate outbreak of Escherichia coli 0157:H7-associated bloody diarrhea and hemolytic uremic syndrome from hamburgers. The Washington experience. JAMA. 1994 Nov 2;272(17):1349-53.
http://www.ncbi.nlm.nih.gov/pubmed/7933395?tool=bestpractice.com
[49]Boyce TG, Swerdlow DL, Griffin PM. Escherichia coli O157:H7 and the hemolytic uremic syndrome. N Engl J Med. 1995 Aug 10;333(6):364-8.
http://www.ncbi.nlm.nih.gov/pubmed/7609755?tool=bestpractice.com
Treatment is primarily supportive. Early intravascular fluid repletion reduces the frequency of oligoanuric acute kidney injury in patients with pre-HUS diarrhoea and appears to improve outcomes in children with diarrhoea-positive HUS.[50]Hickey CA, Beattie TJ, Cowieson J, et al. Early volume expansion during diarrhea and relative nephroprotection during subsequent hemolytic uremic syndrome. Arch Pediatr Adolesc Med. 2011 Oct;165(10):884-9.
https://jamanetwork.com/journals/jamapediatrics/fullarticle/1107613
http://www.ncbi.nlm.nih.gov/pubmed/21784993?tool=bestpractice.com
[51]Ardissino G, Tel F, Possenti I, et al. Early volume expansion and outcomes of hemolytic uremic syndrome. Pediatrics. 2016 Jan;137(1):e20152153.
http://www.ncbi.nlm.nih.gov/pubmed/26644486?tool=bestpractice.com
Meticulous attention should be paid to fluid balance and monitoring urine output; care should be taken to avoid cardiopulmonary overload because these patients are at risk of developing oliguria.[45]Asherson RA, Cervera R, Piette JC, et al. Catastrophic antiphospholipid syndrome: clinical and laboratory features of 50 patients. Medicine (Baltimore). 1998 May;77(3):195-207.
http://www.ncbi.nlm.nih.gov/pubmed/9653431?tool=bestpractice.com
[52]Tarr PI, Neill MA. Escherichia coli O157:H7. Gastroenterol Clin North Am. 2001 Sep;30(3):735-51.
http://www.ncbi.nlm.nih.gov/pubmed/11586555?tool=bestpractice.com
Blood pressure should be monitored and treated if elevated. Hypertension can occur secondary to multiple factors, including volume overload, electrolyte imbalances, and underlying thrombotic microangiopathy affecting the kidneys. Calcium-channel blockers, vasodilators, and beta-blockers can be used in the acute phase for the treatment of hypertension.[53]Siegler RL. The hemolytic uremic syndrome. Pediatr Clin North Am. 1995 Dec;42(6):1505-29.
http://www.ncbi.nlm.nih.gov/pubmed/8614598?tool=bestpractice.com
ACE inhibitors are not generally recommended in the acute setting because of concerns of decreased renal perfusion, but are recommended for patients with end-stage renal disease post HUS.[54]Caletti MG, Lejarraga H, Kelmansky D, et al. Two different therapeutic regimes in patients with sequelae of hemolytic-uremic syndrome. Pediatr Nephrol. 2004 Oct;19(10):1148-52.
http://www.ncbi.nlm.nih.gov/pubmed/15221428?tool=bestpractice.com
[55]Van Dyck M, Proesmans W. Renoprotection by ACE inhibitors after severe hemolytic uremic syndrome. Pediatr Nephrol. 2004 Jun;19(6):688-90.
http://www.ncbi.nlm.nih.gov/pubmed/15064939?tool=bestpractice.com
Systematic reviews have found no significant effect for antibiotic therapy, anti‐Shiga toxin antibody‐containing bovine colostrum, Shiga toxin binding agent (Synsorb Pk), or urtoxazumab (a monoclonal antibody against Shiga toxin) for the secondary prevention of HUS in patients with STEC-associated diarrhoea (very low-quality evidence).[30]Thomas DE, Elliott EJ. Interventions for preventing diarrhea-associated hemolytic uremic syndrome: systematic review. BMC Public Health. 2013 Sep 3;13:799.
https://bmcpublichealth.biomedcentral.com/articles/10.1186/1471-2458-13-799
http://www.ncbi.nlm.nih.gov/pubmed/24007265?tool=bestpractice.com
[56]Imdad A, Mackoff SP, Urciuoli DM, et al. Interventions for preventing diarrhoea-associated haemolytic uraemic syndrome. Cochrane Database Syst Rev. 2021 Jul 5;(7):CD012997.
https://www.cochranelibrary.com/cdsr/doi/10.1002/14651858.CD012997.pub2/full
http://www.ncbi.nlm.nih.gov/pubmed/34219224?tool=bestpractice.com
Although there are insufficient data on the effect of opioids on the course of HUS, cautious use of opioids is advised.
Some interventions may increase risk for HUS and irreversible renal damage.
Avoidance of antibiotics, antimotility (antidiarrhoeal) agents, and non-steroidal anti-inflammatory drugs is advised in children presenting with bloody diarrhoea.
Trimethoprim-sulfamethoxazole showed no significant effect for secondary prevention of HUS in patients with STEC (very low-quality evidence).[30]Thomas DE, Elliott EJ. Interventions for preventing diarrhea-associated hemolytic uremic syndrome: systematic review. BMC Public Health. 2013 Sep 3;13:799.
https://bmcpublichealth.biomedcentral.com/articles/10.1186/1471-2458-13-799
http://www.ncbi.nlm.nih.gov/pubmed/24007265?tool=bestpractice.com
[56]Imdad A, Mackoff SP, Urciuoli DM, et al. Interventions for preventing diarrhoea-associated haemolytic uraemic syndrome. Cochrane Database Syst Rev. 2021 Jul 5;(7):CD012997.
https://www.cochranelibrary.com/cdsr/doi/10.1002/14651858.CD012997.pub2/full
http://www.ncbi.nlm.nih.gov/pubmed/34219224?tool=bestpractice.com
Antibiotic administration for STEC infections is not recommended because of the potentially increased risk for HUS reported in observational studies.[57]Centers for Disease Control and Prevention. E. coli (Escherichia coli). Resources for clinicians and laboratories. Dec 2014 [internet publication].
https://www.cdc.gov/ecoli/clinicians.html
[58]Wong CS, Mooney JC, Brandt JR, et al. Risk factors for the hemolytic uremic syndrome in children infected with Escherichia coli O157:H7: a multivariable analysis. Clin Infect Dis. 2012 Jul;55(1):33-41.
https://academic.oup.com/cid/article/55/1/33/317764
http://www.ncbi.nlm.nih.gov/pubmed/22431799?tool=bestpractice.com
Administration of antimotility agents may increase risk for HUS in patients with diarrhoea caused by STEC infections; worsening clinical condition, including central nervous system (CNS) complications, has been reported.[59]Nelson JM, Griffin PM, Jones TF, et al. Antimicrobial and antimotility agent use in persons with shiga toxin-producing Escherichia coli O157 infection in FoodNet Sites. Clin Infect Dis. 2011 May;52(9):1130-2.
https://academic.oup.com/cid/article/52/9/1130/318071
http://www.ncbi.nlm.nih.gov/pubmed/21467017?tool=bestpractice.com
[60]Shane AL, Mody RK, Crump JA, et al. 2017 Infectious Diseases Society of America clinical practice guidelines for the diagnosis and management of infectious diarrhea. Clin Infect Dis. 2017 Nov 29;65(12):e45-80.
https://academic.oup.com/cid/article/65/12/e45/4557073
http://www.ncbi.nlm.nih.gov/pubmed/29053792?tool=bestpractice.com
[61]Cimolai N, Morrison BJ, Carter JE. Risk factors for the central nervous system manifestations of gastroenteritis-associated hemolytic-uremic syndrome. Pediatrics. 1992 Oct;90(4):616-21.
http://www.ncbi.nlm.nih.gov/pubmed/1408519?tool=bestpractice.com
Platelet transfusions have been associated with clinical deterioration and should be avoided unless there is active bleeding.[62]Bell WR, Braine HG, Ness PM, et al. Improved survival in thrombotic thrombocytopenic purpura-hemolytic uremic syndrome. N Engl J Med. 1991 Aug 8;325(6):398-403.
http://www.ncbi.nlm.nih.gov/pubmed/2062331?tool=bestpractice.com
Red cell transfusion, dialysis, and renal transplantation
Anaemia is common and can be rapid in onset, requiring red cell transfusion. Approximately 50% of patients will require dialysis in the acute phase.[61]Cimolai N, Morrison BJ, Carter JE. Risk factors for the central nervous system manifestations of gastroenteritis-associated hemolytic-uremic syndrome. Pediatrics. 1992 Oct;90(4):616-21.
http://www.ncbi.nlm.nih.gov/pubmed/1408519?tool=bestpractice.com
[63]Siegler RL, Pavia AT, Christofferson RD. A 20-year population-based study of postdiarrheal hemolytic uremic syndrome in Utah. Pediatrics. 1994 Jul;94(1):35-40.
http://www.ncbi.nlm.nih.gov/pubmed/8008534?tool=bestpractice.com
[64]Rowe PC, Orrbine E, Lior H, et al. Risk of hemolytic uremic syndrome after sporadic Escherichia coli O157:H7 infection: results of a Canadian collaborative study. J Pediatr. 1998 May;132(5):777-82.
http://www.ncbi.nlm.nih.gov/pubmed/9602185?tool=bestpractice.com
Patients who develop irreversible acute kidney injury are considered for renal transplantation.
Extra-renal involvement should be assessed, given its contribution to morbidity and mortality:[65]Upadhyaya K, Barwick K, Fishaut M, et al. The importance of nonrenal involvement in hemolytic-uremic syndrome. Pediatrics. 1980 Jan;65(1):115-20.
http://www.ncbi.nlm.nih.gov/pubmed/7355005?tool=bestpractice.com
[66]Grodinsky S, Telmesani A, Robson WL, et al. Gastrointestinal manifestations of hemolytic uremic syndrome: recognition of pancreatitis. J Pediatr Gastroenterol Nutr. 1990 Nov;11(4):518-24.
http://www.ncbi.nlm.nih.gov/pubmed/1702151?tool=bestpractice.com
[67]Rigamonti D, Simonetti GD. Direct cardiac involvement in childhood hemolytic-uremic syndrome: case report and review of the literature. Eur J Pediatr. 2016 Dec;175(12):1927-31.
http://www.ncbi.nlm.nih.gov/pubmed/27659663?tool=bestpractice.com
[68]Benvenuto F, Guillen S, Marchiscio L, et al. Purtscher-like retinopathy in a paediatric patient with haemolytic uraemic syndrome: a case report and literature review. Arch Soc Esp Oftalmol (Engl Ed). 2021 Nov;96(11):607-10.
http://www.ncbi.nlm.nih.gov/pubmed/34756284?tool=bestpractice.com
[69]Mauras M, Bacchetta J, Duncan A, et al. Escherichia coli-associated hemolytic uremic syndrome and severe chronic hepatocellular cholestasis: complication or side effect of eculizumab? Pediatr Nephrol. 2019 Jul;34(7):1289-93.
http://www.ncbi.nlm.nih.gov/pubmed/30963282?tool=bestpractice.com
CNS involvement can lead to stroke or haemorrhage and in rare cases, brain abscesses
Pancreatic involvement, in the form of pancreatitis or acute-onset insulin-dependent diabetes mellitus, can occur, along with bowel infarction, ischaemia, or necrosis
Cardiac involvement in the form of impaired cardiac contractility and myocarditis can occur
Ocular and hepatic involvement, although rare, have been reported in diarrhoea-positive HUS.
Treatment of atypical HUS
Atypical HUS (aHUS) should be suspected when other causes have been ruled out.
Evaluation of the alternative complement pathway can reveal the cause of aHUS. However, to date there is no direct diagnostic test for detecting aHUS.[5]Fakhouri F, Zuber J, Frémeaux-Bacchi V, et al. Haemolytic uraemic syndrome. Lancet. 2017 Aug 12;390(10095):681-96.
http://www.ncbi.nlm.nih.gov/pubmed/28242109?tool=bestpractice.com
The diagnosis of aHUS can be more challenging in adults due to other clinical conditions that can present in a similar fashion. Treatment should not be delayed while awaiting genetic test results; plasma exchange is appropriate in adults (particularly if thrombotic thrombocytopenic purpura remains a possibility).
Eculizumab
A monoclonal antibody that binds to C5 complement protein and blocks terminal complement activation, eculizumab is approved for the management of aHUS in children and adults. Systematic reviews of small non‐randomised, single‐arm studies indicate that eculizumab improves kidney function in patients with aHUS.[70]Rathbone J, Kaltenthaler E, Richards A, et al. A systematic review of eculizumab for atypical haemolytic uraemic syndrome (aHUS). BMJ Open. 2013 Nov 4;3(11):e003573.
https://bmjopen.bmj.com/content/3/11/e003573.long
http://www.ncbi.nlm.nih.gov/pubmed/24189082?tool=bestpractice.com
[71]Menne J, Delmas Y, Fakhouri F, et al. Outcomes in patients with atypical hemolytic uremic syndrome treated with eculizumab in a long-term observational study. BMC Nephrol. 2019 Apr 10;20(1):125.
https://bmcnephrol.biomedcentral.com/articles/10.1186/s12882-019-1314-1
http://www.ncbi.nlm.nih.gov/pubmed/30971227?tool=bestpractice.com
[72]Pugh D, O'Sullivan ED, Duthie FA, et al. Interventions for atypical haemolytic uraemic syndrome. Cochrane Database Syst Rev. 2021 Mar 23;(3):CD012862.
https://www.cochranelibrary.com/cdsr/doi/10.1002/14651858.CD012862.pub2/full
http://www.ncbi.nlm.nih.gov/pubmed/33783815?tool=bestpractice.com
Randomised controlled trials of patients with aHUS are unlikely; careful design of subsequent single-arm trials, in addition to long-term follow-up, are required.[70]Rathbone J, Kaltenthaler E, Richards A, et al. A systematic review of eculizumab for atypical haemolytic uraemic syndrome (aHUS). BMJ Open. 2013 Nov 4;3(11):e003573.
https://bmjopen.bmj.com/content/3/11/e003573.long
http://www.ncbi.nlm.nih.gov/pubmed/24189082?tool=bestpractice.com
[72]Pugh D, O'Sullivan ED, Duthie FA, et al. Interventions for atypical haemolytic uraemic syndrome. Cochrane Database Syst Rev. 2021 Mar 23;(3):CD012862.
https://www.cochranelibrary.com/cdsr/doi/10.1002/14651858.CD012862.pub2/full
http://www.ncbi.nlm.nih.gov/pubmed/33783815?tool=bestpractice.com
Meningococcal prophylaxis is required because there is a risk of infection with encapsulated organisms in patients treated with eculizumab. Eculizumab is contraindicated in patients with unresolved Neisseria meningitidis infection, and in those who are not currently vaccinated against N meningitidis unless the risks of delaying treatment outweigh the risks of developing an infection. Patients who have not been previously vaccinated should be vaccinated against N meningitidis at least 2 weeks before starting treatment with eculizumab. All patients should be re-vaccinated according to current local vaccination guidelines for patients with complement deficiencies.